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Year : 2018  |  Volume : 56  |  Issue : 1  |  Page : 35-37

Juvenile X-Linked retinoschisis: Response to topical dorzolamide therapy

1 Department of Ophthalmology, Uveitis and Neuro-ophthalmology Services, Assam, India
2 Department of Ocular Pathology, Uveitis and Neuro-ophthalmology Services, Assam, India
3 Vitreo-retina Services, Assam, India
4 Medical Retina Services, Assam, India
5 Pediatric Ophthalmology and Strabismus Services, Sri Sankaradeva Nethralaya, Assam, India

Correspondence Address:
Dr. Saurabh Deshmukh
Department of Ophthalmology, Sri Sankaradeva Nethralaya, 96, Basistha Road, Beltola, Guwahati - 781 028, Assam
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Source of Support: None, Conflict of Interest: None

DOI: 10.4103/tjosr.tjosr_35_18

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We report clinical course of a 22-year-old Indian male patient presenting with bilateral Juvenile X-linked retinoschisis (JXLRS) in response to topical 2% dorzolamide hydrochloride treatment. He presented with progressive diminution of vision in both eyes (OU) for the past 16 years. A “cartwheel” macular pattern was observed in his retina OU. Multimodal imaging including fundus photography, fluorescein fundus angiography, optical coherence tomography (OCT), and electroretinogram was performed. Following treatment with topical dorzolamide, there was a significant regression of the macular cyst on OCT and significant improvement in the visual acuity. This case report emphasizes on the response of macular cysts to topical dorzolamide. Thus, it may be a promising treatment option in terms of visual as well as anatomical recovery in JXLRS.

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